dc.contributor.author |
Peláez Chomba, Melissa Sindy |
|
dc.contributor.author |
Vásquez Gómez, Guillermo Raúl |
|
dc.contributor.author |
Sullcahuamán Allende, Yasser Ciro |
|
dc.contributor.author |
Mendoza Fernández, Julio Cesar |
|
dc.contributor.author |
Purizaca Rosillo, Nelson David |
|
dc.contributor.author |
Zevallos, Alejandra |
|
dc.contributor.author |
Cruzate Cabrejos, Vicente Leandro |
|
dc.date.accessioned |
2023-12-05T17:47:58Z |
|
dc.date.available |
2023-12-05T17:47:58Z |
|
dc.date.issued |
2023 |
|
dc.identifier.uri |
https://hdl.handle.net/20.500.12866/14615 |
|
dc.description.abstract |
Osteogenesis imperfecta is considered a rare genetic condition which is characterized by bone fragility. In 85% of cases, it is caused by mutations in COL1A1 and COL1A2 genes which are essential to produce type I collagen. We report the case of a female neonate delivered to a 27-year-old women at San Bartolomé Teaching Hospital with a family history of clavicle fracture. A prenatal control with ultrasound was performed to the mother at 29 weeks. A fetus with altered morphology and multiple fractures was found. Therefore, a prenatal diagnosis of osteogenesis imperfecta was performed. The neonate was born with a respiratory distress syndrome and an acyanotic congenital heart disease. Therefore, she remained in NICU until her death. We highlight the importance of prenatal diagnosis, genetic counseling and a multidisciplinary evaluation in this type of pathologies and report a new probably pathogenic variant in the COL1A2 gene detected by exomic sequencing in amniotic fluid. |
en_US |
dc.language.iso |
eng |
|
dc.publisher |
F1000 Research |
|
dc.relation.ispartofseries |
F1000Research |
|
dc.rights |
info:eu-repo/semantics/restrictedAccess |
|
dc.rights.uri |
https://creativecommons.org/licenses/by-nc-nd/4.0/deed.es |
|
dc.subject |
Osteogenesis imperfecta |
en_US |
dc.subject |
Newborn |
en_US |
dc.subject |
Prenatal diagnosis |
en_US |
dc.subject.mesh |
Osteogénesis Imperfecta |
|
dc.subject.mesh |
Recién Nacido |
|
dc.subject.mesh |
Diagnóstico Prenatal |
|
dc.title |
Case Report: A prenatal diagnosis of osteogenesis imperfecta in a patient with a novel pathogenic variant in COL1A2 |
en_US |
dc.type |
info:eu-repo/semantics/article |
|
dc.identifier.doi |
https://doi.org/10.12688/f1000research.131094.2 |
|
dc.relation.issn |
2046-1402 |
|